Author Information
Channawar
Sarita*, Chamariya Sumit**, Chauhan AR***, Mayadeo
NM****
(*
Assistant Professor, ** Third Year Resident, *** Additional Professor, ****
Professor
Department
of Obstetrics and Gynecology, Seth G.S. Medical
College and K.E.M
Hospital, Mumbai, India.)
Abstract
Developmental anomalies
of the mullerian duct system represent some of the most fascinating and
challenging disorders that gynecologists encounter. This is a report of a
normally menstruating adolescent girl who presented with acute abdominal pain
aggravated during menses. On ultrasonography, she had a septate uterus with
non-communicating unilateral (right-sided) hematometra, a very rare müllerian
anomaly termed as Robert’s uterus; diagnosis was confirmed on magnetic
resonance imaging (MRI). The patient underwent laparotomy with complete
excision of the non-communicating hemiuterus and endometrial cavity with
drainage of hematometra; she recovered completely and resumed painless menses.
The case and relevant literature review are presented.
Introduction
The reported incidence of mullerian duct anomalies (MDAs) is
0.1-3.5%.[1] The most commonly reported anomalies are septate,
arcuate, didelphys, unicornuate, or hypoplastic uteri. The widely accepted
American Fertility Society (AFS) classification organizes MDAs according to
major uterine anatomic defect and allows for standardized reporting methods.
Septate uterus (AFS Class V) is the most common, resulting from incomplete
resorption of the medial septum after complete fusion of the mullerian ducts
has occurred; variations exist like complete, partial and segmental. The
complete septum extends from the fundal area to internal os and divides the
endometrial cavity into 2 components and is often associated with a
longitudinal vaginal septum. The most common presenting symptoms are
dysmenorrhea, dyspareunia, primary or secondary infertility, pregnancy loss and
obstetric complications.
Case Report
A 20 years old unmarried
girl, normally menstruating for 5 years, presented to emergency room with
severe dysmenorrhea. On examination, her secondary sexual characters were
normal. She had mild pallor, marked lower abdominal tenderness but no palpable
lump, and normal external genitalia. On rectal examination, a bulky uterus was
felt in midline, deviated to the right. Transabdominal and transperineal
ultrasonography revealed a septate uterus with right sided hematometra with
normal left endometrial cavity. MRI confirmed the diagnosis and clearly showed
septate uterus with normal left-sided outflow tract with blind right cavity
with septum till internal os and single cervix. There was no communication
between the two cavities; there was no evidence of any renal anomaly. The
noncommunicating horn was considered to be the cause of the patient's severe
dysmenorrhea due to intracavitary retention of menstrual effluent.
Figure 1: MRI showing
Robert’s uterus with right-sided hematometra.
The patient underwent
exploratory laparotomy. The uterus was bulky with normal fundal contour and
well-developed left side, with a soft, bulging right side suggestive of
hematometra. Though right adnexae were normal in appearance, the fallopian tube
was not communicating with the right hemiuterus. An incision was taken over the
right hemiuterus; anchovy sauce-like material of approximately 100 ml was
drained. As the septum was reaching only till internal os, there was neither
communication between lower extent of right hemiuterus and cervix below, nor
with left-side cavity. Hence non-communicating blind right hemiuterus was
excised completely with endometriectomy. The right round ligament was divided; the
bladder pushed inferiorly, extent of incision was up to the internal os
inferiorly and lateral to the midline septum, so as to preserve the normal
functioning left hemiuterus. Intraoperative findings were consistent with
preoperative diagnosis. Uterine incision was sutured in two layers using
delayed absorbable sutures.
Figure 2: Intraoperative
findings
Figure 3: Excision of
right hemiuterus
Figure 4: Uterus after
excision of right hemiuterus and closure
Histopathological
examination was consistent with hematometra. The patient’s postoperative
recovery was uneventful with resumption of normal painless menses in the next
cycle.
Discussion
Robert’s uterus or
asymmetric septate uterus is a rare variant of septate uterus, a unique
congenital mullerian anomaly first reported by Robert in 1970[2]; so
far very few cases have been reported in literature.[3,4,5] This is
characterized by a complete septum, non-communicating hemiuteri with one blind
horn causing hematometra and one communicating hemiuterus with single cervix
and a normal extrauterine morphology. Patients usually present in
postmenarcheal period with unilateral hematometra causing dysmenorrhea. The
modalities for diagnosis are ultrasonography and MRI while
hysterosalpingography, hysteroscopy, and laparoscopy are useful especially in
infertility cases. MRI provides excellent tissue characterization helping in
reliably differentiating septate from bicornuate uterus and also in diagnosing
asymmetric septate uterus.[6,7]
Surgery can be done by
open or minimally invasive method, definitive surgery involves drainage of
hematometra and excision of blind non-communicating hemiuterus taking care to
maintain integrity of functional communicating hemiuterus and cervix.[8,
9]
In order to avoid
inappropriate management, gynecologists should be aware of this rare entity
while evaluating cases of severe dysmenorrhea in previously normal menstruating
young girls. Prompt early diagnosis and surgical correction are essential to
avoid future morbidity due to endometriosis. Few cases have reported successful
pregnancy after endometriectomy in these cases.[10]
References
1.
- Acién P. Incidence of Mullerian defects in fertile and infertile women. Hum Reprod 1997;12(7):1372-6.
- Gupta N, Mittal S, Misra R, A unique congenital mullerian anomaly Robert's uterus. Arch Gynaecol Obstet 2007 Dec;276(6):641-3.
- Capito C, Sarnacki S. Menstrual retention in a Robert's uterus, J Pediatr Adolesc Gynecol 2009 Oct; 22(5):e104-6.
- Benzineb N, Bellasfar M, Merchaoui J, Sfar R. Robert's uterus with menstrual retention in the blind cavity. J Gynaecol Obstet Biol Reprod (Paris),1993;22(4):366-8.
- Rebelo T, Almeida e Sousa LA, Sampaio MG, Martins MJ, et al. Asymmetric septate uterus with unilateral menstrual retention a rare uterine malformation, Acta Med Port, 1997;10(10):721-4.
- Marcal L, Nothaft MA, Coelho F, Volpato R, et al. Mullerian duct anomalies: MR imaging. Abdom Imaging 2011; 36(6):756-64.
- Bermejo C, Martínez Ten P, Cantarero R, Diaz D, Pérez Pedregosa J, Barrón E, Three-dimensional ultrasound in the diagnosis of Mullerian duct anomalies and concordance with magnetic resonance imaging. Ultrasound Obstet Gynecol 2010; 35(5):593-601.
- Takeuchi H, Sato Y, Shimanuki H, Kikuchi I, Kumakiri J, Kitade M, Kinoshita K, Accurate preoperative diagnosis and laparoscopic removal of the cavitated non-communicated uterine horn for obstructive Mullerian anomalies. J Obstet Gynaecol Res 2006;32(1):74-9.
- Perino A, Chianchiano N, Simonaro C, Cittadini E, Endoscopic management of a case of complete septate uterus with unilateral hematometra, Human Reprod 1995;10(8):2171-3.
- Vural M, Yildiz S, Cece H, Camuzcuoglu H. Favourable pregnancy outcome after endometrectomy for a Robert's uterus. J Obstet Gynaecol 2011;31(7):668-9.
Citation
Channawar S, Chamariya
S, Chauhan AR, Mayadeo NM. Robert’s Uterus. JPGO 2014 Volume 1 Number 2 Available from:http://www.jpgo.org/2014/02/roberts-uterus.html