Author
Information
Lothe
S*, Hatkar P**, Satia MN***
(*
Second Year Resident, **Associate Professor, *** Professor,
Department of Obstetrics and Gynecology, Seth G.S. Medical College
and K.E.M. Hospital, Mumbai, India.)
Abstract
Pregnancy
in a woman with sickle cell disease (SCD) is associated with marked
medical as well as obstetrics risk to both the mother and the baby.
Combined efforts of multidisciplinary team including good
obstetrician, expert perinatal team, hematologist and attentive
physician, with a well devised therapeutic plan, in a setting of
comprehensive tertiary care hospital can significantly decrease
maternal and perinatal morbidity and mortality. This is an
illustration of a case of a 27 year old primigravida with 29 weeks
gestation who presented to us in sickle cell crisis, managed
successfully with good maternal and fetal outcome.
Introduction
Sickle
cell disease (SCD) is an
abnormality of red blood cells that may result in circulatory
impairment, tissue damage, severe anemia, infarction and life
threatening infection. Some patients with SCD have no change in
disease activity while some have worsening disease during pregnancy.
Changes in pregnancy like higher metabolic demand, hyper-coagulable
state and vascular stasis may predispose to complications. Factors
like infection, fever, dehydration, cold, overexertion, stress,
acidosis, prolonged labor, operative delivery may precipitate a
sickle cell crisis. A woman with sickle cell disease has higher
chances of maternal and fetal complications as compared to one
without sickle cell disease. Pre-conceptional screening, early
registration, regular prenatal care, good intrapartum and postpartum
management may help to successfully decrease the morbidity and
mortality.
Case
Report
27
years old primigravida with 29 weeks by dates, corresponding by scan,
came to casualty with complaints of severe pain in knee and shoulder
joints associated with backache and fever with chills since four
days. There were no complaints of bleeding from any site. She had
similar complaints on and off since childhood. She was not in labor.
She gave history of pneumonia at 10 years of age for which she was
hospitalized and two units of blood were transfused. Presently
patient was admitted in view of febrile illness with severe
generalized body pain. On general examination she was markedly pale,
there was no lymphadenopathy, JVP was not raised and vital parameters
were stable. On respiratory system examination bilateral basal
crepitations were present. On per abdominal examination uterus was 28
weeks, relaxed, cephalic presentation and fetal heart sounds were
regular. On per vaginal examination os was 1.5 cm dilated, poorly
effaced.
Blood
investigations revealed hemoglobin (Hb) of 5.1 gm%, total white blood
count 46900/mm3 suggestive
of leukemoid reaction, and platelet count of 60000/mm3.
Peripheral smear examination showed sickle cells, tear drop cells,
fragmented red blood cells, Howell Jolly bodies and macrocytes with
basophilic stippling from which inference of sickle cell disease was
drawn. Provisional diagnosis of sickle cell disease with
vaso-occlusive crisis was made. Hemoglobin electrophoresis was done
which was suggestive of sickle cell anemia (HbSS). Conservative and
symptomatic management was started. Adequate hydration, analgesia
with injectable opioids and therapy to prevent acidosis was given,
and intravenous antibiotics were started. TSH was normal. In view of
Hb 5.1 gm% three units of blood were transfused. After 3 days, repeat
investigations were done and Hb was 7.5 gm%, total blood count was
24000/ mm3 and
platelet count was 120000/ mm3.
On
day 5 of admission patient went in spontaneous labor. Adequate
analgesia, oxygenation and hydration were given during labor. Patient
delivered uneventfully, a female baby of 1.090 kg with Apgar score of
9/10. Baby was immediately shifted to neonatal intensive care unit
due to prematurity and low birth weight. Post-delivery investigations
showed raised total white blood counts, hence the patient was stared
on oral antibiotics. Hemoglobin was 8.5 gm%. Patient had fever on
day 3 after delivery thus was switched over to injectable antibiotics
and symptomatic treatment was given. Husband’s sickling test was
done which suggested normal study. The patient was symptomatically
better, fever subsided thus she was discharged on day 10 post
delivery. Baby was kept in neonatal intensive care unit, evaluated
for sickle cell disease, gained weight and discharged on day 21 post
delivery. Baby was found to have sickle cell trait during evaluation.
Patient was counseled regarding future prognosis of baby and was
advised to follow up with the pediatrician.
Discussion
Sickle
cell disease is a group of autosomal recessive disorders which affect
the hemoglobin structure; it is inherited as a single gene defect.[1]
It is the most common inherited
condition worldwide. Most of the pregnancies with sickle cell disease
result in live birth but they are at increased risk of fetomaternal
complications as well as medical complications of sickle cell
disease.[2,3] Vaso-occlusive crisis is the most common complication
that may be encountered in a pregnant woman with sickle cell
disease.[4] The term SCD comprises of sickle cell anemia (HbSS) and
other heterozygous conditions of hemoglobin including combination
with hemoglobin C (HbSC), combination with beta thalassemia (Hb
Thalassemia) and other combinations with D, E or O-Arab. All these
give similar phenotype but severity differs according to the
condition. The combination of
hemoglobin
S with hemoglobin A, known as sickle
cell trait (SA) is asymptomatic except for increased chances of
urinary tract infections in this condition.
SCD has its origin in Sub Saharan
Africa and Middle East, hence it is prevalent in persons of African
descent, southern Europeans, Middle Eastern and Asian Indians. Due to
migrating population, SCD is increasing in importance worldwide.
About 3,00,000 children are born with SCD each year.[5]
Acute
complications in mother include acute chest pain syndrome, ischemic
vaso-occlusive crisis, splenic sequestration, stroke, cholecystitis,
acute renal failure. Chronic complications like chronic pain,
cholelithiasis, retinal problems, pulmonary hypertension, renal
dysfunction, venous thromboembolism can occur.[6] Due to renal
dysfunction, hypertension and placental ischemia, preeclampsia and
eclampsia may occur. Fetal manifestations are due to uteroplacental
insufficiency, opioid exposure for analgesia and alloimmunization.
Studies have documented high risk of intrauterine growth
restriction, preterm birth, low birth weight baby and stillbirth in
cases of SCD. 50-70% of women with sickle cell disease require
hospitalization at least once in their life and 30-40% of them
require blood transfusion.[7] Due to decreased oxygen carrying
capacity of the sickle red blood cells, restricted fetal growth and
maternal organ damage may result. Couple planning for a pregnancy
should be aware of the increased risk to the woman’s health with
SCD during pregnancy. Pre- conception counseling regarding the risks,
mandatory investigations to be done, care during pregnancy and
possible maternal and fetal outcome should be offered to each and
every couple. If the patient is on hydroxyurea it should be stopped
before 3 months of pregnancy or as soon as pregnancy is confirmed.
Pregnancy is contraindicated or if occurs, should be terminated if
the patient has pulmonary hypertension. During pregnancy, complete
blood count, renal and liver function tests, 24 hours urine protein,
retinal examination, 2D Echocardiography to rule out pulmonary
hypertension, BP monitoring should be regularly done. Immunization
should be given to the patient with pneumococcal, influenza type B
and meningococcal vaccines as women with SCD have more
susceptibility to these infections, especially if they have
functional asplenia. Iron levels should be done before giving iron
therapy to the patient. Fetal surveillance should include routine USG
in 1st
and 2nd
trimester, serial USG for growth at interval of 3-4 weeks starting
from 24 weeks and fetal testing at 32 weeks or sooner if indicated.
On
presentation rapid assessment of the patient should be done for
medical complications like sepsis, dehydration, pain crisis or acute
chest syndrome requiring urgent intervention. History should be
revealed if there are any precipitating factors. All mandatory
investigations should be done. Some patients may require blood
transfusion and in some patients prophylactic blood transfusion may
be given to prevent the crisis. If the patient is in pain crisis
aggressive management of pain with opioids should be done.[6]
Adequate hydration, oxygenation and prevention of acidosis should be
done. Various guidelines such as Greentop guidelines by Royal
College of Obstetrics And Gynecology, National Guideline
Clearinghouse guidelines have been given for the management protocol
for SCD in pregnancy. Mode of delivery should be decided according
to the obstetric indications while recognizing that the cesarean
rates are higher in cases with SCD. [2,7,8] Allogenic hematopoietic
stem cell transplantation is the only definitive therapy with
reported overall survival rate of 92 - 94% and event -free survival
rate of 82 - 86%, but it should not be done in pregnancy.[9] In
conclusion, maternal and fetal morbidity secondary to this serious
obstetric problem can be significantly reduced with careful attention
to obstetric and medical details with an expert perinatal team and
well devised plan in a setting of tertiary care.
References
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Lothe S, Hatkar P, Satia MN. JPGO 2015. Successful Pregnancy Outcome In A Case Of Sickle Cell Crisis Volume 3 No. 4. Available from: http://www.jpgo.org/2016/04/successful-pregnancy-outcome-in-case-of.html